DNA-based prenatal diagnosis in a Chinese family with xeroderma pigmentosum group A

Br J Dermatol. 2004 Jun;150(6):1190-3. doi: 10.1111/j.1365-2133.2004.05938.x.

Abstract

Background: Xeroderma pigmentosum (XP) is a group of autosomal recessive diseases characterized by hypersensitivity to ultraviolet rays. Among its eight complementation groups, XP group A (XPA) is the most severe type. The XPAC gene has been identified as the defective gene in XPA patients.

Objectives: To examine genomic DNA from a Chinese family with XPA, to determine the XPAC mutation and, after genetic counselling, to undertake DNA-based prenatal diagnosis in a subsequent pregnancy.

Methods: Fetal DNA was extracted from amniotic fluid and used to amplify exon 5 of XPAC containing the potential mutation. Direct sequencing and restriction endonuclease digestion were used for prenatal diagnosis.

Results: We identified a homozygous nonsense XPAC mutation of 631C-->T, which results in an R211X mutation in XPA protein, in the proband. Both her parents are heterozygous. Prenatal diagnosis demonstrated a heterozygous sequence predicting an unaffected child, and a healthy girl was born.

Conclusions: These data provide the first example of a DNA-based prenatal test for genodermatosis in China.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child, Preschool
  • China
  • Codon, Nonsense*
  • DNA Mutational Analysis
  • DNA-Binding Proteins / genetics*
  • Female
  • Humans
  • Male
  • Pedigree
  • Pregnancy
  • Prenatal Diagnosis / methods*
  • Skin Diseases / diagnosis*
  • Skin Diseases / genetics
  • Xeroderma Pigmentosum / diagnosis*
  • Xeroderma Pigmentosum / genetics
  • Xeroderma Pigmentosum Group A Protein

Substances

  • Codon, Nonsense
  • DNA-Binding Proteins
  • XPA protein, human
  • Xeroderma Pigmentosum Group A Protein