Successful pregnancy in a gonadectomized woman with 46,XY gonadal dysgenesis and gonadoblastoma

Fertil Steril. 2005 Jul;84(1):217. doi: 10.1016/j.fertnstert.2004.11.087.

Abstract

Objective: To present a case of successful pregnancy after conservative bilateral gonadectomy without adjuvant chemotherapy and radiotherapy in a 46,XY gonadal dysgenetic woman with gonadoblastoma and malignant germ cell tumor.

Design: Case report.

Setting: Infertility center in university hospital.

Patient(s): An 18-year-old female with 46,XY karyotype underwent bilateral gonadectomy, and the pathology revealed gonadoblastoma with malignant mixed germ cell tumor.

Intervention(s): Chromosomal analysis, bilateral gonadectomy, donor oocyte, and IVF program.

Main outcome measure(s): Tumor markers and pregnancy result.

Result(s): The patient was free from tumor recurrence after 13 years' follow-up. A successful twin pregnancy was achieved after oocyte donation and IVF.

Conclusion(s): Gonadectomy without adjuvant therapies could be done in 46,XY gonadal dysgenetic women with gonadoblastoma in view of preservation of future fertility.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Female
  • Gonadal Dysgenesis, 46,XY / genetics
  • Gonadal Dysgenesis, 46,XY / surgery*
  • Gonadoblastoma / genetics
  • Gonadoblastoma / surgery*
  • Humans
  • Infant, Newborn
  • Live Birth*
  • Male
  • Ovarian Neoplasms / genetics
  • Ovarian Neoplasms / surgery*
  • Ovariectomy / methods*
  • Pregnancy
  • Pregnancy Outcome
  • Pregnancy, Multiple