An unusual complication of mandibular distraction

Int J Paediatr Dent. 2006 Jan;16(1):55-8. doi: 10.1111/j.1365-263X.2006.00660.x.


Background: The authors present an unusual complication of mandibular distraction in a child with the curious condition of multiple pterygium syndrome is presented.

Case report: The patient was a Caucasian male with severe pterygia in his neck. As a result of his limited mouth opening and restricted upper airway leading to obstruction, he underwent lengthening of his mandible by distraction, which significantly improved his breathing. During his follow-up, it was observed that an unusually elongated permanent molar was present in an abnormal position.

Conclusion: This case highlights the need to carefully plan the sites for osteotomy and the potential for damage to the developing permanent dentition in young children.

Publication types

  • Case Reports

MeSH terms

  • Child, Preschool
  • Contracture / congenital
  • Dental Sac / injuries
  • Follow-Up Studies
  • Humans
  • Male
  • Mandible / abnormalities
  • Mandible / surgery*
  • Molar / abnormalities
  • Neck / abnormalities
  • Osteogenesis, Distraction / adverse effects*
  • Osteogenesis, Distraction / instrumentation
  • Pierre Robin Syndrome / pathology
  • Postoperative Complications*
  • Sleep Apnea, Obstructive / etiology
  • Syndrome
  • Trismus / etiology