Ataxin-2 and its Drosophila homolog, ATX2, physically assemble with polyribosomes

Hum Mol Genet. 2006 Aug 15;15(16):2523-32. doi: 10.1093/hmg/ddl173. Epub 2006 Jul 11.

Abstract

Mutations resulting in the expansion of a polyglutamine tract in the protein ataxin-2 give rise to the neurodegenerative disorders spinocerebellar ataxia type 2 and Parkinson's disease. The normal cellular function of ataxin-2 and the mechanism by which polyglutamine expansion of ataxin-2 causes neurodegeneration are unknown. Here, we demonstrate that ataxin-2 and its Drosophila homolog, ATX2, assemble with polyribosomes and poly(A)-binding protein (PABP), a key regulator of mRNA translation. The assembly of ATX2 with polyribosomes is mediated independently by two distinct evolutionarily conserved regions of ATX2: an N-terminal Lsm/Lsm-associated domain (LsmAD), found in proteins that function in nuclear RNA processing and mRNA decay, and a PAM2 motif, found in proteins that interact physically with PABP. We further show that the PAM2 motif mediates a physical interaction of ATX2 with PABP in addition to promoting ATX2 assembly with polyribosomes. Our results suggest a model in which ATX2 binds mRNA directly through its Lsm/LsmAD domain and indirectly via binding PABP that is itself directly bound to mRNA. These findings, coupled with work on other ataxin-2 family members, suggest that ATX2 plays a direct role in translational regulation. Our results raise the possibility that polyglutamine expansions within ataxin-2 cause neurodegeneration by interfering with the translational regulation of particular mRNAs.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Ataxin-2 / metabolism*
  • Ataxins
  • Cells, Cultured
  • Drosophila / metabolism*
  • Drosophila Proteins / metabolism*
  • Humans
  • Models, Biological
  • Nerve Tissue Proteins / metabolism*
  • Neurodegenerative Diseases / etiology
  • Peptides / metabolism
  • Poly(A)-Binding Proteins / metabolism
  • Polyribosomes / metabolism*
  • Protein Biosynthesis
  • Protein Structure, Tertiary
  • RNA, Messenger / metabolism
  • RNA-Binding Proteins / metabolism

Substances

  • ATX2 protein, Drosophila
  • Ataxin-2
  • Ataxins
  • Drosophila Proteins
  • Nerve Tissue Proteins
  • Peptides
  • Poly(A)-Binding Proteins
  • RNA, Messenger
  • RNA-Binding Proteins
  • polyglutamine