Literature, describing scoliosis in patients of osteogenesis imperfecta (OI), favors operative treatment as soon as possible in the form of fixation with instrumentation and fusion to prevent curve progress and pulmonary function deterioration. There are various complications associated with the treatment of scoliosis in OI before, during, and after surgery because of poor bone quality in such patients. We presented a case report of stress-induced transverse fracture of both iliac wings after scoliosis surgery in a 16-year-old girl with OI, who was treated conservatively. Owing to unusual symptoms and continuous dull pain in her back, the diagnosis was delayed during which the conditions made her life miserable. This report also suggests that a stress fracture should be on high suspicion in OI patients when they present with minor difference in the nature of pain.