Bladder neck contracture after antegrade fulguration of posterior urethral valves has not been reported in English studies to date to the best of our knowledge. A couple of reports have mentioned late-onset bladder neck contracture after retrograde valve fulguration. The present case report describes an unusual complication of bladder neck contracture that occurred long after antegrade fulguration of posterior urethral valves, which was done at an early age. This case report also discusses the possible mechanisms of bladder neck contracture, its management in brief, and highlights the importance of long-term follow-up of these patients.