Acromegaly associated with gangliocytoma

Ir J Med Sci. 2012 Sep;181(3):353-5. doi: 10.1007/s11845-009-0433-2. Epub 2009 Sep 30.

Abstract

Background: Acromegaly secondary to growth hormone-releasing hormone (GHRH) excess is rare.

Aims/case description: We report two patients with acromegaly who were diagnosed with sellar gangliocytomas that were immunopositive for GHRH. Tumour tissue persisted after debulking surgery and in the second case this was associated with persistent growth hormone hypersecretion, successfully suppressed by a somatostatin analogue.

Conclusions: The development of functional pituitary adenomas in association with sellar gangliocytomas is poorly understood. We present a brief discussion of the possible aetiology of these unusual pituitary tumours.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acromegaly / etiology*
  • Adenoma / complications*
  • Adenoma / diagnostic imaging
  • Adenoma / metabolism
  • Ganglioneuroma / complications*
  • Ganglioneuroma / diagnostic imaging
  • Ganglioneuroma / metabolism
  • Growth Hormone-Releasing Hormone / metabolism
  • Humans
  • Male
  • Middle Aged
  • Pituitary Neoplasms / complications*
  • Pituitary Neoplasms / diagnostic imaging
  • Pituitary Neoplasms / metabolism
  • Radiography

Substances

  • Growth Hormone-Releasing Hormone