Kindler syndrome pathogenesis and fermitin family homologue 1 (kindlin-1) function

Dermatol Clin. 2010 Jan;28(1):115-8. doi: 10.1016/j.det.2009.10.012.

Abstract

Kindler syndrome is caused by genetic defects in the focal contact-associated protein, fermitin family homologue 1 (FFH1), encoded by the gene FERMT1 (known as KIND1). Defects in FFH1 lead to abnormal integrin activation and loss of keratinocyte epidermal adhesion to the underlying basal lamina, disruption in normal cell cytoskeleton within keratinocytes, and altered signaling pathways, leading to increased extracellular matrix production. Null mutations in FERMT1 result in skin blistering from birth and early childhood progressive poikiloderma, mucosal fragility, and increased risk of cancer. The complete range of FFH1 functions in skin and other epithelia has yet to be determined.

Publication types

  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • Disease Progression
  • Epidermis / pathology
  • Epidermolysis Bullosa / genetics*
  • Epidermolysis Bullosa / pathology*
  • Humans
  • Membrane Proteins / genetics*
  • Membrane Proteins / physiology*
  • Neoplasm Proteins / genetics*
  • Neoplasm Proteins / physiology*
  • Skin Neoplasms / genetics
  • Skin Neoplasms / pathology
  • Syndrome*

Substances

  • FERMT1 protein, human
  • Membrane Proteins
  • Neoplasm Proteins