Spontaneous pneumomediastinum secondary to refractory dermatomyositis successfully treated with rituximab

Clin Rheumatol. 2010 Aug;29(8):945-6. doi: 10.1007/s10067-010-1399-1. Epub 2010 Mar 1.

Abstract

Spontaneous pneumomediastinum has been described in patients with dermatomyositis (DM) and polymyositis (Korkmaz et al., Rheumatology 40:476-478, 2001; Maruoka et al., Mod Rheumatol 16:55-57, 2006; Kono et al., Ann Rheum Dis 59:372-376, 2000; Neves et al., Clin Rheumatol 26:105-107, 2007). Literature reviews suggest that this complication has a mortality of between 27% and 41% ( Kono et al., Ann Rheum Dis 59:372-376, 2000; Neves et al., Clin Rheumatol 26:105-107, 2007; Goff et al., Arthritis Rheum 61:108-118, 2009). This is the first report of rituximab being used successfully as part of the treatment for DM complicated by pneumomediastinum.

Publication types

  • Case Reports

MeSH terms

  • Antibodies, Monoclonal / therapeutic use*
  • Antibodies, Monoclonal, Murine-Derived
  • Antirheumatic Agents / therapeutic use*
  • Dermatomyositis / complications*
  • Female
  • Humans
  • Mediastinal Emphysema / drug therapy*
  • Mediastinal Emphysema / etiology*
  • Rituximab
  • Treatment Outcome
  • Young Adult

Substances

  • Antibodies, Monoclonal
  • Antibodies, Monoclonal, Murine-Derived
  • Antirheumatic Agents
  • Rituximab