Autosomal dominant Ménétrier-like disease

J Pediatr Gastroenterol Nutr. 2012 Dec;55(6):717-20. doi: 10.1097/MPG.0b013e3182645c2f.

Abstract

Background: Familial occurrence of Ménétrier disease is rare and has been reported only in few instances.

Methods: Affected patients from a large pedigree were evaluated at the clinical, endoscopic, and pathological levels.

Results: Affected members presented with gastropathy of variable severity but without protein loss. Endoscopy and pathology findings were consistent with Ménétrier disease; however, gastric transforming growth factor α (TGF-α) immunohistochemistry and real-time polymerase chain reaction showed no increase in TGF-α expression.

Conclusions: We describe a unique, 4-generation pedigree with autosomal dominant gastropathy exhibiting the typical clinical, endoscopic, and pathological findings of Ménétrier-like disease, though in the absence of protein loss and with no increase in the levels of gastric TGF-α. Members of this family may be affected by a novel and previously unrecognised hereditary form of gastric hyperplasia.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Case-Control Studies
  • Child, Preschool
  • Family
  • Female
  • Gastric Mucosa / metabolism
  • Gastritis, Hypertrophic / genetics*
  • Gastritis, Hypertrophic / metabolism
  • Genes, Dominant*
  • Humans
  • Hyperplasia
  • Male
  • Pedigree
  • Proteins / metabolism*
  • Stomach / pathology*
  • Transforming Growth Factor alpha / metabolism*

Substances

  • Proteins
  • Transforming Growth Factor alpha