A blueprint for research on Shankopathies: a view from research on autism spectrum disorder

Dev Neurobiol. 2014 Feb;74(2):85-112. doi: 10.1002/dneu.22150. Epub 2013 Dec 17.

Abstract

Autism spectrum disorders (ASD) are associated with mutations in a host of genes including a number that function in synaptic transmission. Phelan McDermid syndrome involves mutations in SHANK3 which encodes a protein that forms a scaffold for glutamate receptors at the synapse. SHANK3 is one of the genes that underpins the synaptic hypothesis for ASD. We discuss this hypothesis with a view to the broader context of ASD and with special emphasis on highly penetrant genetic disorders including Shankopathies. We propose a blueprint for near and longer-term goals for fundamental and translational research on Shankopathies.

Keywords: Shank3; autism; neurodevelopmental disorders; synaptic genes.

Publication types

  • Review

MeSH terms

  • Animals
  • Child
  • Child Development Disorders, Pervasive / genetics*
  • Child Development Disorders, Pervasive / physiopathology
  • Child Development Disorders, Pervasive / therapy
  • Forecasting
  • Gene-Environment Interaction
  • Humans
  • Models, Neurological
  • Nerve Tissue Proteins / genetics*
  • Nerve Tissue Proteins / metabolism
  • Research / trends
  • Synaptic Transmission / physiology

Substances

  • Nerve Tissue Proteins
  • SHANK1 protein, human
  • SHANK2 protein, human
  • SHANK3 protein, human