Juvenile manifestation of ultrasound communication deficits in the neuroligin-4 null mutant mouse model of autism

Behav Brain Res. 2014 Aug 15:270:159-64. doi: 10.1016/j.bbr.2014.05.019. Epub 2014 May 20.

Abstract

Neuroligin-4 (Nlgn4) is a member of the neuroligin family of postsynaptic cell adhesion molecules. Loss-of-function mutations of NLGN4 are among the most frequent, known genetic causes of heritable autism. Adult Nlgn4 null mutant (Nlgn4(-/-)) mice are a construct valid model of human autism, with both genders displaying a remarkable autistic phenotype, including deficits in social interaction and communication as well as restricted and repetitive behaviors. In contrast to adults, autism-related abnormalities in neonatal and juvenile Nlgn4(-/-) mice have not been reported yet. The present study has been designed to systematically investigate in male and female Nlgn4(-/-) pups versus wildtype littermates (WT, Nlgn4(+/+)) developmental milestones and stimulus-induced ultrasound vocalization (USV). Neonatal development, followed daily from postnatal days (PND) 4 to 21, including physical development, neurological reflexes and neuromotor coordination, did not yield any differences between Nlgn4(-/-) and their WT littermates. USV in pups (PND8-9) in response to brief separation from their mothers revealed remarkable gender effects, and a genotype influence in females regarding latency to first call. In juveniles (PND22-23), USV monitoring upon exposure to an anesthetized female intruder mouse uncovered a clear genotype effect with reduced USV in Nlgn4(-/-) mice, and again a more prominent phenotype in females. Together, these data support an early manifestation of communication deficits in Nlgn4(-/-) mice that appear more pronounced in immature females with their overall stronger USV as compared to males.

Keywords: C57BL/6J; Gender; Neonatal development; Neonatal milestones; Neuroligin-4; Ultrasound or ultrasonic vocalization.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Age Factors
  • Animals
  • Autistic Disorder / genetics
  • Autistic Disorder / physiopathology*
  • Autistic Disorder / psychology*
  • Behavior, Animal
  • Cell Adhesion Molecules, Neuronal / deficiency*
  • Communication*
  • Disease Models, Animal
  • Female
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Mice, Knockout
  • Motor Activity
  • Phenotype
  • Sex Factors
  • Social Behavior
  • Stereotyped Behavior
  • Ultrasonics / methods
  • Vocalization, Animal*

Substances

  • Cell Adhesion Molecules, Neuronal
  • Nlgn4 protein, mouse