Genetic features of metachronous esophageal cancer developed in Hodgkin's lymphoma or breast cancer long-term survivors: an exploratory study

PLoS One. 2015 Jan 22;10(1):e0117070. doi: 10.1371/journal.pone.0117070. eCollection 2015.

Abstract

Background: Development of novel therapeutic drugs and regimens for cancer treatment has led to improvements in patient long-term survival. This success has, however, been accompanied by the increased occurrence of second primary cancers. Indeed, patients who received regional radiotherapy for Hodgkin's Lymphoma (HL) or breast cancer may develop, many years later, a solid metachronous tumor in the irradiated field. Despite extensive epidemiological studies, little information is available on the genetic changes involved in the pathogenesis of these solid therapy-related neoplasms.

Methods: Using microsatellite markers located in 7 chromosomal regions frequently deleted in sporadic esophageal cancer, we investigated loss of heterozygosity (LOH) and microsatellite instability (MSI) in 46 paired (normal and tumor) samples. Twenty samples were of esophageal carcinoma developed in HL or breast cancer long-term survivors: 14 squamous cell carcinomas (ESCC) and 6 adenocarcinomas (EADC), while 26 samples, used as control, were of sporadic esophageal cancer (15 ESCC and 11 EADC).

Results: We found that, though the overall LOH frequency at the studied chromosomal regions was similar among metachronous and sporadic tumors, the latter exhibited a statistically different higher LOH frequency at 17q21.31 (p = 0.018). By stratifying for tumor histotype we observed that LOH at 3p24.1, 5q11.2 and 9p21.3 were more frequent in ESCC than in EADC suggesting a different role of the genetic determinants located nearby these regions in the development of the two esophageal cancer histotypes.

Conclusions: Altogether, our results strengthen the genetic diversity among ESCC and EADC whether they occurred spontaneously or after therapeutic treatments. The presence of histotype-specific alterations in esophageal carcinoma arisen in HL or breast cancer long-term survivors suggests that their transformation process, though the putative different etiological origin, may retrace sporadic ESCC and EADC carcinogenesis.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adenocarcinoma / genetics*
  • Adenocarcinoma / radiotherapy
  • Adult
  • Aged
  • Breast Neoplasms / genetics*
  • Breast Neoplasms / radiotherapy
  • Carcinoma, Squamous Cell / genetics*
  • Carcinoma, Squamous Cell / radiotherapy
  • Esophageal Neoplasms / genetics*
  • Female
  • Hodgkin Disease / genetics*
  • Hodgkin Disease / radiotherapy
  • Humans
  • Loss of Heterozygosity*
  • Male
  • Microsatellite Repeats*
  • Middle Aged
  • Neoplasms, Second Primary / genetics*
  • Survivors*

Grants and funding

This work was supported by the following grants: Associazione Italiana per la Ricerca sul Cancro (AIRC, Ref. 10430), Ministero della Istruzione, della Università e della Ricerca (MIUR, Prot. 2010MCLPLB-003); AA received the funding. The funders had no role in study design, data collection and analysis, decision to publish, or preparation of the manuscript.