Celiac disease evolving into dermatitis herpetiformis in patients adhering to normal or gluten-free diet

Scand J Gastroenterol. 2015 Apr;50(4):387-92. doi: 10.3109/00365521.2014.974204. Epub 2015 Feb 1.

Abstract

Objective: Dermatitis herpetiformis (DH) is a cutaneous form of celiac disease affecting ∼ 17% of celiac disease patients. The aim was to determine how often celiac disease precedes the development of DH, and what is the impact of gluten-free diet (GFD) in this phenotype change.

Material and methods: Our prospectively collected DH series from 1970 comprised 514 patients. We analyzed all DH patients who at least 2 years earlier had been diagnosed with celiac disease. DH diagnosis was confirmed by showing immunoglobulin A deposits in dermis. Serological and small bowel mucosal findings were analyzed, and the strictness of GFD treatment before and after the diagnosis of DH was evaluated.

Results: Twenty (4%) DH patients had a prior diagnosis of celiac disease. The median time interval between celiac disease and DH detection was 9.5 years. Before DH appeared 4 patients had been on a normal gluten-containing diet, 10 had dietary lapses on a GFD, and 6 were on a strict GFD. Celiac autoantibodies were positive in 7 out of 19 patients, and 5 out of 7 undergoing small bowel biopsy had partial villous atrophy. Following DH diagnosis the rash was controlled after a median of 6 months on a strict GFD.

Conclusions: Patients with celiac disease may develop DH by time. This is most often an indicator of poor adherence to GFD, and a rigorous dietary intervention is necessary. In the majority of cases, DH will be detected without prior celiac disease diagnosis, but the physicians should recognize this phenotype alteration.

Keywords: celiac disease; dermatitis herpetiformis; follow-up; gluten-free diet.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Atrophy
  • Autoantibodies / blood
  • Celiac Disease / complications
  • Celiac Disease / diet therapy*
  • Celiac Disease / pathology
  • Child
  • Child, Preschool
  • Dermatitis Herpetiformis / blood
  • Dermatitis Herpetiformis / complications
  • Dermatitis Herpetiformis / diet therapy*
  • Diet, Gluten-Free*
  • Female
  • Humans
  • Infant
  • Intestinal Mucosa / pathology*
  • Male
  • Middle Aged
  • Patient Compliance
  • Phenotype*
  • Time Factors
  • Young Adult

Substances

  • Autoantibodies