• Perineal groove is described as a wet sulcus lined with mucoumembrane extending from the posterior fourchette to the anterior anus • Perineal grooves are rarely described in literature but ar likely more common in practice. • The underlying pathogenesis and embryologic origin of perineal grooves are poorly understood. • Perineal grooves generally self-resolve by 1 year of age. • Surgical intervention is rarely indicated but can be considered for rare complications (infections, mucus drainage) or for cosmetic purposes, usually after 2 years of age. • Recognition of this mild anomaly can eliminate unnecessary (and potentially invasive) testing and procedures.