A functional ATG16L1 (T300A) variant is associated with necrotizing enterocolitis in premature infants

Pediatr Res. 2017 Apr;81(4):582-588. doi: 10.1038/pr.2016.260. Epub 2016 Nov 28.

Abstract

Background: The genetic basis of dysfunctional immune responses in necrotizing enterocolitis (NEC) remains unknown. We hypothesized that variants in nucleotide binding and oligomerization domain (NOD)-like receptors (NLRs) and autophagy (ATG) genes modulate vulnerability to NEC.

Methods: We genotyped a multi-center cohort of premature infants with and without NEC for NOD1, NOD2, ATG16L1, CARD8, and NLRP3 variants. Chi-square tests and logistic regression were used for statistical analysis.

Results: In our primary cohort (n = 1,015), 86 (8.5%) infants developed NEC. The A allele of the ATG16L1 (Thr300Ala) variant was associated with increased NEC (AA vs. AG vs. GG; 11.3 vs. 8.4 vs. 4.8%, P = 0.009). In regression models for NEC that adjusted for epidemiological confounders, GA (P = 0.033) and the AA genotype (P = 0.038) of ATG16L1 variant were associated with NEC. The association between the A allele of the ATG16L1 variant and NEC remained significant among Caucasian infants (P = 0.02). In a replication cohort (n = 259), NEC rates were highest among infants with the AA genotype but did not reach statistical significance.

Conclusion: We report a novel association between a hypomorphic variant in an autophagy gene (ATG16L1) and NEC in premature infants. Our data suggest that decreased autophagy arising from genetic variants may confer protection against NEC.

MeSH terms

  • Alleles
  • Autophagy*
  • Autophagy-Related Proteins / genetics*
  • Carrier Proteins / genetics
  • Cohort Studies
  • Enterocolitis, Necrotizing / genetics*
  • Female
  • Genetic Predisposition to Disease
  • Genetic Variation
  • Genotype
  • Humans
  • Infant, Newborn
  • Infant, Premature*
  • Polymorphism, Single Nucleotide
  • White People

Substances

  • ATG16L1 protein, human
  • Autophagy-Related Proteins
  • Carrier Proteins