Molecular composition and distribution of gap junctions in the sensory epithelium of the human cochlea-a super-resolution structured illumination microscopy (SR-SIM) study

Ups J Med Sci. 2017 Aug;122(3):160-170. doi: 10.1080/03009734.2017.1322645. Epub 2017 May 17.

Abstract

Background: Mutations in the GJB2 gene, which encodes the Connexin26 (Cx26) protein, are the most common cause of childhood hearing loss in American and European populations. The cochlea contains a gap junction (GJ) network in the sensory epithelium and two connective tissue networks in the lateral wall and spiral limbus. The syncytia contain the GJ proteins beta 2 (GJB2/Cx26) and beta 6 (GJB6/Cx30). Our knowledge of their expression in humans is insufficient due to the limited availability of tissue. Here, we sought to establish the molecular arrangement of GJs in the epithelial network of the human cochlea using surgically obtained samples.

Methods: We analyzed Cx26 and Cx30 expression in GJ networks in well-preserved adult human auditory sensory epithelium using confocal, electron, and super-resolution structured illumination microscopy (SR-SIM).

Results: Cx30 plaques (<5 μm) dominated, while Cx26 plaques were subtle and appeared as 'mini-junctions' (2-300 nm). 3-D volume rendering of Z-stacks and orthogonal projections from single optical sections suggested that the GJs are homomeric/homotypic and consist of assemblies of identical GJs composed of either Cx26 or Cx30. Occasionally, the two protein types were co-expressed, suggesting functional cooperation.

Conclusions: Establishing the molecular composition and distribution of the GJ networks in the human cochlea may increase our understanding of the pathophysiology of Cx-related hearing loss. This information may also assist in developing future strategies to treat genetic hearing loss.

Keywords: Cochlea; SR-SIM; confocal microscopy; connexin 26/30; human.

MeSH terms

  • Adult
  • Cochlea / metabolism*
  • Connexins / metabolism
  • Epithelium / metabolism
  • Female
  • Gap Junctions / metabolism*
  • Gap Junctions / ultrastructure
  • Humans
  • Immunohistochemistry
  • Male
  • Microscopy, Confocal / methods*
  • Microscopy, Electron, Transmission
  • Middle Aged

Substances

  • Connexins

Grants and funding

Our research was conducted as part of the European Community Research human stem cell applications for the treatment of hearing loss project (Grant Agreement No. 603029; project acronym: OTOSTEM). This study was also supported by ALF grants from Uppsala University Hospital and Uppsala University and by the ‘Tysta Skolan’ Foundation, the Sellanders Foundation, the Swedish Deafness Foundation (HRF), and the Austrian Science Foundation (FWF) (Grant No. 21848-N13). We also acknowledge the kind donations of private funds by Börje Runögård and David Giertz, Sweden.