The usefulness of advanced lipid and oxidative stress testing for diagnosis and management of low HDL-cholesterol phenotype: A case report

Clin Biochem. 2017 Dec;50(18):1323-1325. doi: 10.1016/j.clinbiochem.2017.06.007. Epub 2017 Jun 23.

Abstract

Objective: Plasma high-density lipoprotein cholesterol (HDL-C) level is a strong inverse predictor of cardiovascular disease (CVD) development. Tangier disease, a consequence of mutations in the ATP binding cassette transporter 1 (ABCA1) gene, is associated with very low HDL-C levels. Still, the relationship between Tangier disease and CVD is not always evident. The study investigates usefulness of lipoprotein subfractions, oxidative stress and paraoxonase 1 (PON1) status assessment for evaluation and management of patient with low HDL-C phenotype.

Patient and methods: A 12-year-old boy was hospitalised due to hypertension. Laboratory evaluation revealed low HDL-C level, and subsequent molecular diagnostic confirmed Tangier disease. Lipoprotein subfractions were assessed by gradient-gel electrophoresis. Oxidative stress status was estimated by measuring total antioxidative status, total oxidative status, prooxidative-antioxidative balance, malondialdehyde and advanced oxidation protein products levels. Activity of paraoxonase 1 in serum and its distribution within HDL subclasses was also determined (ten healthy boys aged 13.1±3.4years served as the reference group).

Results: Analysis of oxidative stress status biomarkers revealed a state of prolonged prooxidants activity. In turn, serum PON1 activity was substantially reduced. The majority of PON1 activity was present on HDL 2 particles.

Conclusion: Impaired antioxidative potential of HDL may point toward hidden cardiovascular risk in isolated low HDL-phenotype.

Keywords: HDL subclasses; Oxidative stress; PON1 status; Small, dense LDL; Tangier disease.

Publication types

  • Case Reports

MeSH terms

  • ATP Binding Cassette Transporter 1 / genetics
  • ATP Binding Cassette Transporter 1 / metabolism
  • Aryldialkylphosphatase / genetics
  • Aryldialkylphosphatase / metabolism
  • Child
  • Cholesterol, HDL / blood*
  • Cholesterol, HDL / genetics
  • Humans
  • Lipid Peroxidation*
  • Male
  • Oxidative Stress*
  • Tangier Disease / blood*
  • Tangier Disease / genetics
  • Tangier Disease / therapy*

Substances

  • ABCA1 protein, human
  • ATP Binding Cassette Transporter 1
  • Cholesterol, HDL
  • Aryldialkylphosphatase
  • PON1 protein, human