Fatal CTLA-4 heterozygosity with autoimmunity and recurrent infections: a de novo mutation

Clin Case Rep. 2017 Nov 6;5(12):2066-2070. doi: 10.1002/ccr3.1257. eCollection 2017 Dec.

Abstract

Primary immunodeficiency disorders are rarely diagnosed in adults but must be considered in the differential diagnosis of combined recurrent infections and autoimmune disease. We describe a patient with CTLA-4 haploinsufficiency and an abnormal regulatory T-cell phenotype. Unusually, infections were more severe than autoimmunity, illustrating therapeutic challenges in disease course.

Keywords: CTLA‐4 mutation; Evans syndrome; hypogammaglobulinemia; sepsis.

Publication types

  • Case Reports