Aggressive laryngeal fibromatosis: A case report and brief review

J Cancer Res Ther. 2018 Jan-Mar;14(2):465-467. doi: 10.4103/0973-1482.183554.

Abstract

We describe a rare case of aggressive fibromatosis of the larynx occurring in a 72-year-old man. The lesion manifested with complaints of dyspnea and stridor. A computerized tomographic scan of the neck revealed irregular polypoidal growth invading right vocal cord, crossing midline. A malignant tumor was suspected. Although several laryngoscopy-driven biopsies were negative for malignancy, total laryngectomy was done since the lesion was not deemed amenable to conservative therapy. Tissue sections featured a moderately cellular lesion composed of spindle cells with bland, elongated nuclei, enmeshed in a variably collagenized ground substance. The spindle cells were immunopositive for vimentin and negative for cytokeratins, PGP-9.5, smooth muscle antigen, CD68, desmin, and S-100 protein and Ki-67 of 4%. No further therapy was administered. Based on the available literature, our data confirm that aggressive laryngeal fibromatosis in adult patients is a locally infiltrating disease. Total laryngectomy with clear margins is needed as to avoid the high risk of local recurrence.

Keywords: Aggressive fibromatosis; extra-abdominal fibromatosis; larynx.

Publication types

  • Case Reports
  • Letter
  • Review

MeSH terms

  • Aged
  • Biomarkers
  • Biopsy
  • Desmoid Tumors / diagnosis*
  • Desmoid Tumors / therapy*
  • Humans
  • Immunohistochemistry
  • Laryngeal Neoplasms / diagnosis*
  • Laryngeal Neoplasms / therapy*
  • Laryngectomy
  • Male
  • Tomography, X-Ray Computed
  • Treatment Outcome

Substances

  • Biomarkers