A Refractory Case of Secondary Membranous Nephropathy Concurrent with IgG4-related Tubulointerstitial Nephritis

Intern Med. 2018 Oct 1;57(19):2873-2877. doi: 10.2169/internalmedicine.0836-18. Epub 2018 Apr 27.

Abstract

A 58-year-old man with type 1 autoimmune pancreatitis was referred to nephrologists for severe proteinuria. Laboratory data revealed a high serum IgG4 level, hypoalbuminemia, and massive proteinuria, which were compatible with nephrotic syndrome. The renal pathological findings confirmed the diagnosis of secondary membranous nephropathy concurrent with IgG4-related tubulointerstitial nephritis. Despite the improvement of interstitial markers, the proteinuria was refractory to prednisolone, requiring cyclosporine to achieve complete remission. Membranous nephropathy is a rare manifestation of IgG4-related kidney disease. This case shows that the therapeutic response to prednisolone significantly differs between glomerular lesions and interstitial lesions of IgG4-related kidney disease.

Keywords: IgG-subclass; IgG4-related kidney disease; M-type phospholipase A2 receptor (PLA2R); membranous nephropathy; tubulointerstitial nephritis.

Publication types

  • Case Reports

MeSH terms

  • Anti-Inflammatory Agents / therapeutic use
  • Cyclosporine / therapeutic use
  • Glomerulonephritis, Membranous / complications*
  • Glomerulonephritis, Membranous / diagnosis*
  • Glomerulonephritis, Membranous / therapy
  • Humans
  • Immunoglobulin G / blood
  • Immunoglobulin G4-Related Disease / diagnosis*
  • Immunoglobulin G4-Related Disease / etiology
  • Immunosuppressive Agents / therapeutic use
  • Male
  • Middle Aged
  • Nephritis, Interstitial / diagnosis*
  • Nephritis, Interstitial / therapy
  • Nephrotic Syndrome / diagnosis*
  • Nephrotic Syndrome / etiology
  • Nephrotic Syndrome / therapy
  • Pancreatitis / complications*
  • Prednisolone / therapeutic use
  • Proteinuria / diagnosis
  • Proteinuria / etiology
  • Proteinuria / therapy

Substances

  • Anti-Inflammatory Agents
  • Immunoglobulin G
  • Immunosuppressive Agents
  • Cyclosporine
  • Prednisolone