Abstract
Terminal deletions of long arm of chromosome 13 are rare and poorly characterized by cytogenetic studies, making for difficult genotype-phenotype correlations. We report two siblings presenting generalized epilepsy, intellectual disability, and genitourinary tract defects. Array CGH detected a 1.3 Mb deletion at 13q34; it contains two protein-coding genes, SOX1 and ARHGEF7, whose haploinsufficiency can contribute to the epileptic phenotype.
Keywords:
13q34 deletion; ARHGEF7; Epilepsy; SOX1.
Copyright © 2018 British Epilepsy Association. Published by Elsevier Ltd. All rights reserved.
MeSH terms
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Brain / drug effects
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Brain / physiopathology
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Child
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Chromosome Deletion*
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Chromosomes, Human, Pair 13*
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Epilepsy, Generalized / drug therapy
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Epilepsy, Generalized / genetics*
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Epilepsy, Generalized / pathology
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Epilepsy, Generalized / physiopathology
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Face / abnormalities
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Humans
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Infant
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Intellectual Disability / genetics*
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Intellectual Disability / pathology
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Intellectual Disability / physiopathology
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Male
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Phenotype
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Rho Guanine Nucleotide Exchange Factors / genetics
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SOXB1 Transcription Factors / genetics
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Siblings
Substances
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ARHGEF7 protein, human
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Rho Guanine Nucleotide Exchange Factors
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SOX1 protein, human
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SOXB1 Transcription Factors