Constitutive Activation of the Canonical NF-κB Pathway Leads to Bone Marrow Failure and Induction of Erythroid Signature in Hematopoietic Stem Cells

Cell Rep. 2018 Nov 20;25(8):2094-2109.e4. doi: 10.1016/j.celrep.2018.10.071.

Abstract

Constitutive activation of the canonical NF-κB pathway has been associated with a variety of human pathologies. However, molecular mechanisms through which canonical NF-κB affects hematopoiesis remain elusive. Here, we demonstrate that deregulated canonical NF-κB signals in hematopoietic stem cells (HSCs) cause a complete depletion of HSC pool, pancytopenia, bone marrow failure, and premature death. Constitutive activation of IKK2 in HSCs leads to impaired quiescence and loss of function. Gene set enrichment analysis (GSEA) identified an induction of "erythroid signature" in HSCs with augmented NF-κB activity. Mechanistic studies indicated a reduction of thrombopoietin (TPO)-mediated signals and its downstream target p57 in HSCs, due to reduced c-Mpl expression in a cell-intrinsic manner. Molecular studies established Klf1 as a key suppressor of c-Mpl in HSPCs with increased NF-κB. In essence, these studies identified a previously unknown mechanism through which exaggerated canonical NF-κB signals affect HSCs and cause pathophysiology.

Keywords: NF-kB; bone marrow failure; erythroid differentiation; hematopoietic stem cells; pancytopenia; self-renewal; signal transduction; transcription factors.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Animals
  • Bone Marrow / metabolism*
  • Cell Cycle
  • Cytokines / genetics
  • Cytokines / metabolism
  • Erythroid Cells / metabolism*
  • Hematopoietic Stem Cells / metabolism*
  • I-kappa B Kinase / metabolism
  • Inflammation Mediators / metabolism
  • Kruppel-Like Transcription Factors / metabolism
  • Mice
  • Mutation / genetics
  • NF-kappa B / metabolism*
  • Pancytopenia / pathology
  • Signal Transduction*
  • Transcription, Genetic

Substances

  • Cytokines
  • Inflammation Mediators
  • Kruppel-Like Transcription Factors
  • NF-kappa B
  • erythroid Kruppel-like factor
  • I-kappa B Kinase
  • Ikbkb protein, mouse