Photosensitive epilepsy: Robust clinical efficacy of a selective GABA potentiator

Neurology. 2019 Apr 9;92(15):e1786-e1795. doi: 10.1212/WNL.0000000000007271. Epub 2019 Mar 15.

Abstract

Objective: The objective of this phase 2a study was to assess the activity of PF-06372865, a positive allosteric modulator (PAM) of α2/3/5 subunit-containing GABAA receptors with minimal activity at α1-containing receptors, which are believed to mediate many of the adverse events associated with benzodiazepines, in the epilepsy photosensitivity model as a proof-of-principle of efficacy.

Methods: Seven participants with a photoparoxysmal response to intermittent photic stimulation (IPS) at baseline were randomized in a double-blind, 4-period cross-over study examining single doses of 17.5 and 52.5 mg PF-06372865, 2 mg lorazepam (active control), and placebo. Standardized photosensitivity ranges (SPRs) to IPS were recorded at screening, predose, and 1, 2, 4, and 6 hours postdose. The primary endpoint was the average least squares mean change in the SPR in the participant's most sensitive eye condition, across all time points.

Results: Both doses of PF-06372865 produced a marked and statistically significant mean reduction in SPR compared to placebo, which was similar in degree to lorazepam. There was complete suppression of SPR in 6/7 participants following PF-06372865 or lorazepam administration. PF-06372865 was safe and well-tolerated.

Conclusion: PF-06372865 demonstrated highly robust efficacy. This demonstrates anticonvulsant activity of a novel α2/3/5-subtype selective GABAA PAM in humans. Further study of the antiepileptic properties of PF-06372865 is warranted.

Clinicaltrialsgov identifier: NCT02564029.

Classification of evidence: This study provides Class II evidence that for people with a stable photoparoxysmal response to intermittent photic stimulation, PF-06372865 reduces the SPR.

Publication types

  • Clinical Trial, Phase II
  • Multicenter Study
  • Randomized Controlled Trial
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Anticonvulsants / adverse effects
  • Anticonvulsants / pharmacokinetics
  • Anticonvulsants / therapeutic use*
  • Cross-Over Studies
  • Dose-Response Relationship, Drug
  • Double-Blind Method
  • Epilepsy, Reflex / drug therapy*
  • Female
  • GABA Modulators / therapeutic use
  • GABA-A Receptor Agonists / adverse effects
  • GABA-A Receptor Agonists / pharmacokinetics
  • GABA-A Receptor Agonists / therapeutic use*
  • Humans
  • Imidazoles / adverse effects
  • Imidazoles / pharmacokinetics
  • Imidazoles / therapeutic use*
  • Lorazepam / therapeutic use
  • Male
  • Middle Aged
  • Pyridazines / adverse effects
  • Pyridazines / pharmacokinetics
  • Pyridazines / therapeutic use*
  • Treatment Outcome
  • Young Adult

Substances

  • Anticonvulsants
  • GABA Modulators
  • GABA-A Receptor Agonists
  • Imidazoles
  • PF-06372865
  • Pyridazines
  • Lorazepam

Associated data

  • ClinicalTrials.gov/NCT02564029