Frontotemporal Dermal Sinus Tract with 2 Connected Intradiploic Dermoid Cysts: A Rare Case and Review of the Literature

World Neurosurg. 2019 Jul:127:350-353. doi: 10.1016/j.wneu.2019.03.222. Epub 2019 Mar 28.


Background: Frontotemporal dermal sinus tracts with associated dermoid cysts are very rare, with only 1 found in the largest series to date and 10 total documented case reports.

Case description: We present the first case to our knowledge of a dermal sinus tract associated with 2 intradiploic dermoid cysts in the rare location of the pterion and sphenosquamosal suture. The patient was a 15-month-old girl presenting with periorbital cellulitis who was found to have 2 connected intradiploic cysts on radiographic imaging. The mass was excised, and pathology was consistent with a ruptured dermoid cyst.

Conclusions: We review of the literature and argue for early identification and prophylactic surgical resection to avoid complications associated with infection and to mitigate risk of subtotal resection.

Keywords: Abscess; Dermoid cyst; Frontotemporal tract; Intradiploic.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Dermoid Cyst / complications
  • Dermoid Cyst / diagnostic imaging
  • Dermoid Cyst / surgery*
  • Female
  • Frontal Lobe / diagnostic imaging
  • Frontal Lobe / surgery*
  • Humans
  • Infant
  • Spina Bifida Occulta / diagnostic imaging
  • Spina Bifida Occulta / surgery*
  • Temporal Lobe / diagnostic imaging
  • Temporal Lobe / surgery*