[Tandem mass spectrometry analysis and genetic diagnosis of neonates with fatty acid oxidation disorders in central and northern regions of Guangxi]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2019 Nov 10;36(11):1067-1072. doi: 10.3760/cma.j.issn.1003-9406.2019.11.003.
[Article in Chinese]

Abstract

Objective: To determine the incidence and mutational types of fatty acid oxidation disorders (FAOD) in central-northern region of Guangxi.

Methods: A total of 62 953 neonates were screened for FAOD during December 2012 and December 2017. Acyl-carnitine profiling of neonatal blood sample was performed by tandem mass spectrometry using dry blood spots on a filter paper. The diagnosis of FAOD was confirmed by organic acid profiling of urea and genetic testing.

Results: Eighteen cases of FAOD were diagnosed among the 62 953 neonates. Among these, primary carnitine deficiency (PCD) was the most common type (n=13), which was followed by short-chain acyl-CoA dehydrogenase deficiency (SCADD) (n=2), medium-chain acyl-CoA dehydrogenase deficiency (MCADD) (n=1), multiple acyl-CoA dehydrogenase deficiency (MADD) (n=1), and carnitine palmitoyltransferase II deficiency (CPT II D) (n=1). Genetic testing has revealed two previously unreported variants, i.e., c.337G to A (p.Gly113Arg) of ACADS gene and c.737G TO T (p.Gly246Val) of ETFA gene.

Conclusion: PCD is the most common FAOD in central-northern Guangxi. Tandem mass spectrometry combined with genetic testing may facilitate early diagnosis of FAOD.

MeSH terms

  • Acyl-CoA Dehydrogenase / deficiency
  • Acyl-CoA Dehydrogenase / genetics
  • Carnitine / blood
  • Carnitine O-Palmitoyltransferase / deficiency
  • China
  • Electron-Transferring Flavoproteins / genetics
  • Humans
  • Infant, Newborn
  • Lipid Metabolism, Inborn Errors / diagnosis*
  • Lipid Metabolism, Inborn Errors / genetics*
  • Metabolism, Inborn Errors / diagnosis
  • Multiple Acyl Coenzyme A Dehydrogenase Deficiency / diagnosis
  • Neonatal Screening
  • Tandem Mass Spectrometry

Substances

  • ETFA protein, human
  • Electron-Transferring Flavoproteins
  • Acyl-CoA Dehydrogenase
  • Carnitine O-Palmitoyltransferase
  • Carnitine

Supplementary concepts

  • Carnitine palmitoyl transferase 2 deficiency
  • Short chain Acyl CoA dehydrogenase deficiency