Outcome of fetal Vein Galen aneurysmal malformations: a systematic review and meta-analysis

J Matern Fetal Neonatal Med. 2022 Dec;35(25):5312-5317. doi: 10.1080/14767058.2021.1878494. Epub 2021 Jan 28.

Abstract

Objectives: To report the outcome of fetuses with a prenatal diagnosis of Vein of Galen (VOG) malformation.

Methods: PubMed and Embase databases were searched. Random effect meta-analysis of proportions was used to analyze the data. The outcomes explored were prenatal ultrasound findings, mortality, preterm birth (PTB), abnormal neurological outcome, associated findings detected at post-natal brain imaging, need for anticonvulsant therapy, and the rate of children free from neurological impairment. Random effect meta-analysis of proportions were used to analyze the data.

Results: Eleven studies (226 fetuses with a prenatal diagnosis of VOG malformation) were included. All cases were detected during the third trimester of pregnancy. Ventriculomegaly was detected in 31.8% (95% CI 27.6-47.7), cardiomegaly or other ultrasound signs of cardiac compromise in 23.1% (95% CI 14.9-32.5) and hydrops in 7.3% (95% CI 2.8-13.6) of cases. The incidence of IUD, NND, and PND was 1.5% (95% CI 0.2-4.3), 23.8% (95% CI 16.9-31.4), and 24.5% (95% CI 17.6-32.2), respectively, while 12.6% (95% CI 6.0-21.2) of pregnancies were complicated by PTB. Abnormal neurodevelopmental outcome was observed in 36.7% (95% CI 27.9-39.7) of cases, while 60.5% (95% CI 17.0-82.0) of children had abnormal findings on post-natal imaging and only 29.7% (95% CI 23.3-36.5) were free from neurological impairment after birth, although there was a wide heterogeneity in the time at follow-up between the included studies.

Conclusion: VOG malformation diagnoses during fetal life is associated with a high incidence of brain damage, cardiac compromise, and abnormal neurodevelopmental outcome after birth.

Keywords: Vein of Galen; aneurysmal; artero-venous malformation; cardiomegaly; hydrops; prosencephalic vein; ventriculomegaly.

Publication types

  • Meta-Analysis
  • Systematic Review

MeSH terms

  • Cerebral Veins*
  • Female
  • Humans
  • Infant, Newborn
  • Nervous System Malformations*
  • Pregnancy
  • Premature Birth*
  • Prenatal Diagnosis / methods
  • Ultrasonography, Prenatal / methods
  • Vein of Galen Malformations* / complications
  • Vein of Galen Malformations* / diagnostic imaging