Joint status and related risk factors in patients with severe hemophilia A: a single-center cross-sectional study

Hematology. 2022 Dec;27(1):80-87. doi: 10.1080/16078454.2021.2019892.

Abstract

Objectives: Hemophilic arthropathy is the most common complication of severe hemophilia A. This study aims to investigated joint status and related risk factors in patients with severe hemophilia A (PWSHA).

Methods: This single-center study included 31 patients. Six index joints (both elbows, knees, and ankles) were evaluated using the Hemophilia Early Arthropathy Detection with UltraSound in China (HEAD-US-C) and Hemophilia Joint Health Score (HJHS). Treatment adherence was measured using the Validated Hemophilia Regimen Treatment Adherence Scale-Prophylaxis (VERITAS-Pro). We analyzed the influence of age, treatment delay (the interval between diagnosis and the initiation of treatment), prophylaxis, and treatment adherence on joint outcomes.

Results: All patients were male (median age, 22 years). The median age at diagnosis was 1 year; that at initial treatment was 5 years. All patients experienced joint bleeding. HEAD-US-C and HJHS scores were positively correlated (R = 0.70, P < 0.0001). Median [range] HEAD-US-C and HJHS scores were 15 [0-36] and 32 [2-49], respectively. Age was positively correlated with both HEAD-US-C (P = 0.002) and HJHS scores (P < 0.0001). The difference of HEAD-US-C scores between groups with ≤1 year and >1 year treatment delay was close to significant (P = 0.055). HJHS scores were significantly different between these two groups (P = 0.03). Joint assessment scores were not significantly different between on-demand and low-dose prophylaxis groups. VERITAS-Pro scores were correlated with both HEAD-US-C and HJHS scores (P = 0.046 and P = 0.005, respectively).

Conclusions: Hemophilic arthropathy was pervasive in PWSHA. Age and poor adherence were significantly correlated with joint damage. Prompt treatment and adherence improvement may reduce severity.

Keywords: Hemophilia A; hemarthrosis; joint diseases; medication adherence; prophylaxis; quality of life.

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Child, Preschool
  • Cross-Sectional Studies
  • Delayed Diagnosis
  • Disease Management
  • Disease Susceptibility
  • Hemarthrosis / epidemiology*
  • Hemarthrosis / etiology*
  • Hemarthrosis / therapy
  • Hemophilia A / complications*
  • Hemophilia A / diagnosis
  • Hemophilia A / epidemiology*
  • Hemophilia A / therapy
  • Humans
  • Male
  • Risk Assessment
  • Risk Factors
  • Young Adult