Japanese pediatric patient with refractory steroid-resistant ulcerative colitis successfully treated with Tofacitinib: A case report

Medicine (Baltimore). 2022 Nov 11;101(45):e31757. doi: 10.1097/MD.0000000000031757.

Abstract

Rationale: Tofacitinib is an orally administered selective Janus kinase inhibitor. Its efficacy and safety in adults with moderately to severely active ulcerative colitis (UC) have been evaluated in clinical trials; however, its efficacy in pediatric patients with UC is limited.

Patient concerns: A 9-years-old boy was referred to our hospital with chief complaints of diarrhea and bloody stool for 2 months. Colonoscopy revealed total colitis-type UC. His pediatric UC activity index score was 40, indicating moderately active UC.

Diagnosis: UC.

Interventions: Vedolizumab, golimumab, and ustekinumab were introduced because of steroid-resistant refractory UC; however, none of these biologics were effective or the effect was short-lived. Therefore, tofacitinib was administered 5 mg twice a day.

Outcomes: The patient achieved UC remission after tofacitinib treatment, leading to maintained remission without adverse events.

Lessons: To the best of our knowledge, this is the first pediatric case of moderately active UC that was successfully treated with tofacitinib in Japan. Tofacitinib is a safe drug for pediatric patients with moderately active UC. Even in steroid-dependent cases refractory to other biologics, tofacitinib can result in remission induction and maintenance effects. In children and adults, high-dose tofacitinib during induction therapy may be unnecessary to reduce adverse events.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Biological Factors / therapeutic use
  • Biological Products* / therapeutic use
  • Child
  • Colitis, Ulcerative* / drug therapy
  • Humans
  • Japan
  • Male
  • Steroids / therapeutic use

Substances

  • tofacitinib
  • Biological Factors
  • Steroids
  • Biological Products