[Diagnosis of a patient with Spinocerebellar ataxia type 29 due to a novel variant of ITPR1 gene]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2023 Jan 10;40(1):76-80. doi: 10.3760/cma.j.cn511374-20220110-00022.
[Article in Chinese]

Abstract

Objective: To explore the clinical and genetic characteristics of a child with spinocerebellar ataxia type 29 (SCA29) due to novel variant of the inositol 1,4,5-trisphosphate receptor type 1 (ITPR1) gene.

Methods: The child was subjected high-throughput sequencing, and candidate variant was verified by Sanger sequencing of his family members.

Results: The child was found to harbor a c.800C>T (p.T267M) variant of the ITPR1 gene, which was not found in his parents and their fetus. The variant has occurred in a hotspot of the ITPR1 gene variants and was unreported before in China. Based on his clinical and genetic characteristics, the child was diagnosed with SCA29.

Conclusion: The novel heterozygous c.800C>T (p.T267M) of the ITPR1 gene probably underlay the SCA29 in this child.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Child
  • Family
  • Humans
  • Inositol 1,4,5-Trisphosphate Receptors* / genetics
  • Mutation
  • Spinocerebellar Ataxias* / diagnosis
  • Spinocerebellar Ataxias* / genetics
  • Spinocerebellar Degenerations*

Substances

  • Inositol 1,4,5-Trisphosphate Receptors
  • ITPR1 protein, human

Supplementary concepts

  • Spinocerebellar Ataxia 29