Protocadherin 20 maintains intestinal barrier function to protect against Crohn's disease by targeting ATF6

Genome Biol. 2023 Jul 5;24(1):159. doi: 10.1186/s13059-023-02991-0.

Abstract

Background: Intestinal barrier dysfunction plays a central role in the pathological onset of Crohn's disease. We identify the cadherin superfamily member protocadherin 20 (PCDH20) as a crucial factor in Crohn's disease. Here we describe the function of PCDH20 and its mechanisms in gut homeostasis, barrier integrity, and Crohn's disease development.

Results: PCDH20 mRNA and protein expression is significantly downregulated in the colonic epithelium of Crohn's disease patients and mice with induced colitis compared with controls. In mice, intestinal-specific Pcdh20 knockout causes defects in enterocyte proliferation and differentiation, while causing morphological abnormalities. Specifically, the deletion disrupts barrier integrity by unzipping adherens junctions via β-catenin regulation and p120-catenin phosphorylation, thus aggravating colitis in DSS- and TNBS-induced colitis mouse models. Furthermore, we identify activating transcription factor 6 (ATF6), a key chaperone of endoplasmic reticulum stress, as a functional downstream effector of PCDH20. By administering a selective ATF6 activator, the impairment of intestinal barrier integrity and dysregulation of CHOP/β-catenin/p-p120-catenin pathway was reversed in Pcdh20-ablated mice with colitis and PCDH20-deficient colonic cell lines.

Conclusions: PCDH20 is an essential factor in maintaining intestinal epithelial homeostasis and barrier integrity. Specifically, PCDH20 helps to protect against colitis by tightening adherens junctions through the ATF6/CHOP/β-catenin/p-p120-catenin axis.

Keywords: ATF6; Adherens junctions; Crohn’s disease; Endoplasmic reticulum stress; Intestinal barrier integrity; PCDH20.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Activating Transcription Factor 6 / metabolism
  • Animals
  • Colitis* / chemically induced
  • Colitis* / pathology
  • Crohn Disease*
  • Delta Catenin
  • Intestinal Mucosa / metabolism
  • Mice
  • Protocadherins
  • beta Catenin / metabolism

Substances

  • Activating Transcription Factor 6
  • beta Catenin
  • Delta Catenin
  • Protocadherins
  • PCDH20 protein, human
  • ATF6 protein, human