Primary adenocarcinoma arising from rectal implantation cyst after low anterior resection for rectal cancer 31 years previously

Clin J Gastroenterol. 2024 Oct;17(5):899-903. doi: 10.1007/s12328-024-02002-0. Epub 2024 Jun 10.

Abstract

Rectal implantation cysts can occur at anastomotic sites after low anterior resection (LAR) for rectal cancer. Herein, we report a case of primary adenocarcinoma arising from a rectal implantation cyst after LAR for rectal cancer. A 70-year-old woman was referred to our hospital for diagnosis and treatment of a growing cystic lesion. She had LAR performed for rectal cancer 29 years previously and had a rectal implantation cyst detected 13 years previously. On the first visit to our hospital, serum CEA and CA19-9 levels were elevated, and computed tomography (CT) scans revealed a cystic lesion near the anastomosis. CT-guided biopsy revealed no cancer tissue in the cystic lesion. After that, the cystic lesion naturally shrank, and serum CEA and CA19-9 levels became normal. Follow-up included 3 monthly serum CEA and CA19-9 testing and 6 monthly CT scans. Two years later, serum CEA and CA19-9 levels were elevated again. Colonoscopy revealed an ulcerative lesion at the anastomotic site, in which adenocarcinoma was confirmed. Abdominoperineal resection with sacral resection was performed, and postoperative histopathological examination revealed a primary adenocarcinoma with mucinous component at the implantation cyst. Since rectal implantation cysts can become malignant after extended periods, clinicians need to be aware of this disease.

Keywords: Adenocarcinoma; Implantation cyst; Low anterior resection; Rectal cancer.

Publication types

  • Case Reports

MeSH terms

  • Adenocarcinoma* / diagnosis
  • Adenocarcinoma* / pathology
  • Adenocarcinoma* / surgery
  • Aged
  • Anastomosis, Surgical
  • CA-19-9 Antigen / blood
  • Carcinoembryonic Antigen / blood
  • Cysts* / diagnostic imaging
  • Cysts* / etiology
  • Cysts* / pathology
  • Cysts* / surgery
  • Female
  • Humans
  • Postoperative Complications / etiology
  • Proctectomy
  • Rectal Diseases / etiology
  • Rectal Diseases / pathology
  • Rectal Diseases / surgery
  • Rectal Neoplasms* / pathology
  • Rectal Neoplasms* / surgery
  • Tomography, X-Ray Computed

Substances

  • Carcinoembryonic Antigen
  • CA-19-9 Antigen