Role of Cholesterol Metabolic Enzyme CYP46A1 and Its Metabolite 24S-Hydroxycholesterol in Ischemic Stroke

Stroke. 2024 Oct;55(10):2492-2501. doi: 10.1161/STROKEAHA.124.047803. Epub 2024 Sep 3.

Abstract

Background: For several decades, it has been recognized that overactivation of the glutamate-gated N-methyl-D-aspartate receptors (NMDARs) and subsequent Ca2+ toxicity play a critical role in ischemic brain injury. 24S-hydroxycholesterol (24S-HC) is a major cholesterol metabolite in the brain, which has been identified as a potent positive allosteric modulator of NMDAR in rat hippocampal neurons. We hypothesize that 24S-HC worsens ischemic brain injury via its potentiation of the NMDAR, and reducing the production of 24S-HC by targeting its synthetic enzyme CYP46A1 provides neuroprotection.

Methods: We tested this hypothesis using electrophysiological, pharmacological, and transgenic approaches and in vitro and in vivo cerebral ischemia models.

Results: Our data show that 24S-HC potentiates NMDAR activation in primary cultured mouse cortical neurons in a concentration-dependent manner. At 10 µmol/L, it dramatically increases the steady-state currents by 51% and slightly increases the peak currents by 20%. Furthermore, 24S-HC increases NMDA and oxygen-glucose deprivation-induced cortical neuronal injury. The increased neuronal injury is largely abolished by NMDAR channel blocker MK-801, suggesting an NMDAR-dependent mechanism. Pharmacological inhibition of CYP46A1 by voriconazole or gene knockout of Cyp46a1 dramatically reduces ischemic brain injury.

Conclusions: These results identify a new mechanism and signaling cascade that critically impacts stroke outcome: CYP46A1 → 24S-HC → NMDAR → ischemic brain injury. They offer proof of principle for further development of new strategies for stroke intervention by targeting CYP46A1 or its metabolite 24S-HC.

Keywords: 24-hydroxycholesterol; brain ischemia; cholesterol; cholesterol 24-hydroxylase; stroke.

MeSH terms

  • Animals
  • Brain Ischemia / metabolism
  • Cells, Cultured
  • Cholesterol / metabolism
  • Cholesterol 24-Hydroxylase* / metabolism
  • Hydroxycholesterols* / metabolism
  • Hydroxycholesterols* / pharmacology
  • Ischemic Stroke* / metabolism
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Mice, Knockout
  • Neurons / drug effects
  • Neurons / metabolism
  • Receptors, N-Methyl-D-Aspartate* / metabolism

Substances

  • Cholesterol 24-Hydroxylase
  • 24-hydroxycholesterol
  • Hydroxycholesterols
  • Receptors, N-Methyl-D-Aspartate
  • Cholesterol