Effectiveness and safety of tofacitinib versus calcineurin inhibitor in interstitial lung disease secondary to anti-MDA5-positive dermatomyositis: a multicentre cohort study

Eur Respir J. 2025 May 22;65(5):2401488. doi: 10.1183/13993003.01488-2024. Print 2025 May.

Abstract

Objective: To compare the effectiveness and safety of tofacitinib versus calcineurin inhibitor (CNI) as initial immunosuppressive regimen for anti-melanoma differentiation-associated gene 5-positive dermatomyositis with interstitial lung disease (MDA5+DM-ILD).

Methods: Adult Chinese patients with newly diagnosed MDA5+DM-ILD (ILD course <3 months) from five tertiary referral centres between April 2014 and January 2023 were included in this retrospective cohort study. The primary effectiveness end-point was lung transplantation-free survival within 1 year. Propensity score-based inverse probability of treatment weighting (IPTW) was applied for adjustment in this real-world study.

Results: In the eligible cohort, a total of 94 (32.4%) and 105 (46.7%) patients died or underwent lung transplantation within 1 year in the tofacitinib group (n=290) and the CNI group (n=225), respectively. After adjustment by IPTW, patients' lung transplantation-free survival rate within 1 year was significantly higher in the tofacitinib group compared to the CNI group (log-rank p=0.013). Multivariable Cox analysis performed in the IPTW dataset revealed that the hazard ratio of tofacitinib versus CNI for 1-year survival was 0.72 (95% CI 0.56-0.94; p=0.013). The adjusted difference of survival rate was 9.3% (95% CI 2.8-15.8%). Alternative analytic strategies yielded consistent results in sensitivity analyses. Patients aged <60 years, without rapidly progressive ILD, or with baseline arterial oxygen tension/inspiratory oxygen fraction ≥300 mmHg might benefit more from tofacitinib. Opportunistic infection was the major treatment-related serious adverse event, with generally comparable incidence (42.4% versus 45.3%).

Conclusion: In this large multicentre cohort study, tofacitinib showed significantly more benefits for 1-year lung transplantation-free survival than calcineurin inhibitors in MDA5+DM-ILD.

Publication types

  • Multicenter Study
  • Comparative Study

MeSH terms

  • Adult
  • Aged
  • Calcineurin Inhibitors* / adverse effects
  • Calcineurin Inhibitors* / therapeutic use
  • Dermatomyositis* / complications
  • Dermatomyositis* / drug therapy
  • Dermatomyositis* / immunology
  • Female
  • Humans
  • Immunosuppressive Agents* / adverse effects
  • Immunosuppressive Agents* / therapeutic use
  • Interferon-Induced Helicase, IFIH1 / immunology
  • Lung Diseases, Interstitial* / drug therapy
  • Lung Diseases, Interstitial* / etiology
  • Lung Diseases, Interstitial* / immunology
  • Lung Diseases, Interstitial* / mortality
  • Lung Transplantation
  • Male
  • Middle Aged
  • Piperidines* / therapeutic use
  • Propensity Score
  • Proportional Hazards Models
  • Protein Kinase Inhibitors / therapeutic use
  • Pyrimidines* / adverse effects
  • Pyrimidines* / therapeutic use
  • Retrospective Studies
  • Treatment Outcome

Substances

  • tofacitinib
  • Calcineurin Inhibitors
  • Piperidines
  • Pyrimidines
  • Interferon-Induced Helicase, IFIH1
  • IFIH1 protein, human
  • Immunosuppressive Agents
  • Protein Kinase Inhibitors