Estimation of mosaic loss of Y chromosome cell fraction with genotyping arrays lacking coverage in the pseudoautosomal region

BMC Bioinformatics. 2025 Feb 19;26(1):60. doi: 10.1186/s12859-025-06076-6.

Abstract

Background: Mosaic loss of the Y chromosome (mLOY) in circulating leukocytes is the most frequently detected age-related chromosomal mosaic event in men. Current mLOY detection approaches use genotyping arrays and employ a phase-based approach that identifies B allele frequency (BAF) deviations in the pseudo-autosomal region (PAR) shared between the X and Y chromosome. As some widely used genotyping arrays lack sufficient probe coverage of the PAR, methods for accurately measuring mLOY utilizing the median log2 R ratio across the male-specific region of Y chromosome (mLRR_Y) are needed for detecting mLOY on these platforms.

Results: We derived a formula from mLRR_Y to estimate the cellular fraction (CF) of cells with Y loss and validated the approach, finding high alignment with the CF estimation from female data and lab-generated qPCR data (R2 = 0.98). Additionally, we compared the correlation between phase-based BAF and mLRR_Y methods for CF estimation, achieving a high correlation with R2 > 0.80.

Conclusion: Although mLRR_Y is a noisier metric for mosaic chromosomal alteration detection relative to BAF, we demonstrate mLRR_Y across non-PAR variants can accurately estimate mLOY CF, especially for high CF mLOY.

Keywords: Cell fraction; Detection; Log2 R ratio; Mosaic loss of Y chromosome; Y chromosome.

MeSH terms

  • Chromosomes, Human, Y* / genetics
  • Female
  • Gene Frequency / genetics
  • Genotype
  • Genotyping Techniques / methods
  • Humans
  • Male
  • Mosaicism*
  • Pseudoautosomal Regions / genetics