An HTLV-1-Infected Humanized Mouse Model Expressing HLA-A*02:01 Demonstrates Effective CTL-Mediated Suppression of HTLV-1

Viruses. 2025 Sep 16;17(9):1249. doi: 10.3390/v17091249.

Abstract

Human T-cell leukemia virus type 1 (HTLV-1) establishes lifelong infection and is associated with severe diseases such as adult T-cell leukemia/lymphoma (ATL) and HTLV-1-associated myelopathy/tropical spastic paraparesis (HAM/TSP). Cytotoxic T lymphocytes (CTLs), especially those specific for the viral protein Tax, play a pivotal role in controlling HTLV-1 infection. However, conventional humanized mouse models fail to fully reconstitute human immune responses, limiting their utility for evaluating CTL-mediated immunity. This study aimed to establish a physiologically relevant in vivo model to investigate human CTL responses against HTLV-1. To achieve this, we utilized NOG-HLA-A02 transgenic (Tg) mice expressing human HLA-A02:01 on thymic epithelial cells, enabling proper development of HLA-restricted human T cells. Compared to conventional humanized NOG mice, HTLV-1-infected humanized NOG-HLA-A02 Tg mice exhibited significantly reduced HTLV-1 proviral load (PVL), decreased expansion of infected CD4+ T cells, a trend toward increased frequencies of Tax-specific CD8+ T cells, and prolonged survival. These results demonstrate that the expression of HLA-A02:01 facilitates robust CTL-mediated immune control of HTLV-1. This model provides a powerful platform for dissecting HTLV-1 immunopathogenesis and evaluating CTL-targeted therapeutic strategies, including vaccines and immune checkpoint inhibitors.

Keywords: HLA; HTLV-1; Tax-specific CTLs; humanized mouse.

MeSH terms

  • Animals
  • CD8-Positive T-Lymphocytes / immunology
  • Disease Models, Animal
  • Gene Products, tax / immunology
  • HLA-A2 Antigen* / genetics
  • HLA-A2 Antigen* / immunology
  • HTLV-I Infections* / immunology
  • HTLV-I Infections* / virology
  • Human T-lymphotropic virus 1* / immunology
  • Humans
  • Mice
  • Mice, Transgenic
  • T-Lymphocytes, Cytotoxic* / immunology

Substances

  • HLA-A2 Antigen
  • HLA-A*02:01 antigen
  • Gene Products, tax