The Tbx1 ortholog org-1 is required to establish testis stem cell niche identity in Drosophila

Development. 2026 Jan 1;153(1):dev204914. doi: 10.1242/dev.204914. Epub 2026 Jan 8.

Abstract

Stem cells require signals from a cellular microenvironment known as the niche that regulates identity, location and division of stem cells. Niche cell identity must be properly specified during development to form a tissue capable of functioning in the adult. Here, we show that the Tbx1 ortholog org-1 is expressed in Drosophila testis niche cells in response to Slit and FGF signals. org-1 is expressed during niche development and is required to specify niche cell identity. org-1 mutants specified fewer niche cells, and those cells showed disruption of niche-specific markers, including loss of the niche adhesion protein Fas3 and reduced hedgehog expression. We found that org-1 expression in somatic gonadal precursors is capable of inducing formation of additional niche cells. Disrupted niche identity in org-1 mutants caused defects in niche assembly and functionality. We found that the conserved transcription factor islet is expressed in response to org-1 and show that islet functions downstream to mediate niche identity and assembly. This work identifies a previously unreported role for org-1 in niche establishment.

Keywords: Drosophila; Gonadogenesis; Niche identity; Org1; Stem cell niche; Tbx1.

MeSH terms

  • Animals
  • Drosophila Proteins* / genetics
  • Drosophila Proteins* / metabolism
  • Drosophila melanogaster* / cytology
  • Drosophila melanogaster* / genetics
  • Drosophila melanogaster* / metabolism
  • Drosophila*
  • Gene Expression Regulation, Developmental
  • Hedgehog Proteins / metabolism
  • Male
  • Mutation
  • Signal Transduction
  • Stem Cell Niche* / physiology
  • Stem Cells* / cytology
  • Stem Cells* / metabolism
  • T-Box Domain Proteins* / genetics
  • T-Box Domain Proteins* / metabolism
  • Testis* / cytology
  • Testis* / metabolism
  • Transcription Factors / genetics
  • Transcription Factors / metabolism

Substances

  • Drosophila Proteins
  • T-Box Domain Proteins
  • Transcription Factors
  • Hedgehog Proteins