DNA methylation triage of human papillomavirus-positive atypical squamous cells of undetermined significance in cervical cancer screening

J Obstet Gynaecol. 2026 Dec;46(1):2623828. doi: 10.1080/01443615.2026.2623828. Epub 2026 Feb 2.

Abstract

Background: Triage of human papillomavirus (HPV)-positive women with atypical squamous cells of undetermined significance (ASC-US) remains a longstanding clinical challenge in cervical cancer screening, as conventional strategies often lead to excessive colposcopy referrals. We conducted a diagnostic cohort study of 195 HPV-positive women who underwent ASC-US cytology.

Methods: Multigene DNA methylation analysis was performed on residual cervical exfoliated cells, using histology from colposcopy-directed biopsy and/or endocervical sampling as the reference standard to minimise colposcopy referrals.

Results: Our results showed that methylation levels of PAX1, EPB41L3, and FAM19A4 increased progressively from ≤ CIN1 to CIN2, CIN3, and cervical cancer, with significant decreases in ΔCt values from ≤ CIN1 to CIN3 for all three genes (p < 0.05). For detection of CIN2+, the assay achieved a sensitivity of 85.19%, specificity of 96.43%, positive predictive value (PPV) of 79.31%, negative predictive value (NPV) of 97.59%, and an area under the receiver operating characteristic curve (AUC) of 0.91, thereby avoiding colposcopy referrals in 96.43% (162/168). For CIN3+, the assay demonstrated sensitivity, specificity, PPV, NPV, and AUC values of 94.44%, 93.22%, 58.62%, 99.4%, and 0.94, respectively. Stratified analyses showed high and comparable sensitivity (81.82% vs. 87.50%), specificity (96.92% vs. 96.12%), and AUC (0.89 vs. 0.92) in women with HPV16/18 compared with those with non-16/18 high-risk HPV. Optimal diagnostic accuracy was observed in women aged ≥30 years, with sensitivities ranging from 85.70% to 100%, specificities from 94.44% to 100%, and AUC values ranging from 0.93 to 0.97. In contrast, the performance was suboptimal in women aged <30 years (sensitivity, 33.33%; AUC, 0.64).

Conclusions: The host multigene DNA methylation assay demonstrates high specificity and good sensitivity for triaging HPV-positive ASC-US women, with the potential to reduce colposcopy referrals while maintaining robust detection of high-grade lesions, particularly in those aged ≥30 years.

Keywords: ASC-US; DNA methylation; HPV; biomarker; cervical cancer.

Plain language summary

In cervical cancer screening, management of human papillomavirus-positive individuals with atypical squamous cells of undetermined significance presents a clinical challenge, as the routine approach of direct referral for colposcopy often results in many patients undergoing unnecessary invasive procedures. In this study, we applied a combined multigene DNA methylation assay in this population, using histology as the gold standard. The results demonstrated that the assay accurately stratifies high- and low-risk groups, enables more than 96% of low-risk individuals to avoid colposcopy, and shows optimal performance in women aged ≥30 years. Overall, this assay is an effective tool for achieving precise triage, as it not only optimises cervical cancer screening pathways but also substantially reduces medical burden and psychological anxiety.

MeSH terms

  • Adult
  • Atypical Squamous Cells of the Cervix* / pathology
  • Atypical Squamous Cells of the Cervix* / virology
  • Cohort Studies
  • Colposcopy
  • Cytokines
  • DNA Methylation*
  • Early Detection of Cancer* / methods
  • Female
  • Human Papillomavirus Viruses* / genetics
  • Human Papillomavirus Viruses* / isolation & purification
  • Humans
  • Microfilament Proteins
  • Middle Aged
  • Paired Box Transcription Factors / genetics
  • Papillomavirus Infections* / diagnosis
  • Predictive Value of Tests
  • Sensitivity and Specificity
  • Triage / methods
  • Uterine Cervical Dysplasia* / diagnosis
  • Uterine Cervical Dysplasia* / genetics
  • Uterine Cervical Dysplasia* / pathology
  • Uterine Cervical Dysplasia* / virology
  • Uterine Cervical Neoplasms* / diagnosis
  • Uterine Cervical Neoplasms* / genetics
  • Uterine Cervical Neoplasms* / pathology
  • Uterine Cervical Neoplasms* / virology

Substances

  • PAX1 transcription factor
  • EPB41L3 protein, human
  • TAFA4 protein, human
  • Paired Box Transcription Factors
  • Microfilament Proteins
  • Cytokines