Pancytopenia in mannosidosis

Arch Intern Med. 1983 Jun;143(6):1266-8.

Abstract

A case of autoimmune pancytopenia is described in a patient with mannosidosis who developed anti-platelet and anti-neutrophil antibodies and a low haptoglobin level. Bone marrow biopsy and 111InCl3 bone marrow scanning demonstrated hypoplasia of the marrow with a paucity of "storage cells." Pathogenic mechanisms and implications for other inborn errors of metabolism are discussed.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Blood Platelets / immunology
  • Bone Marrow Examination
  • Carbohydrate Metabolism, Inborn Errors / complications*
  • Haptoglobins / analysis
  • Humans
  • Male
  • Mannose / metabolism*
  • Mannosidases / deficiency
  • Neutrophils / immunology
  • Pancytopenia / etiology*
  • Pancytopenia / immunology
  • Pancytopenia / pathology

Substances

  • Haptoglobins
  • Mannosidases
  • Mannose