Retained intraocular cilia embedded in the retina are extremely rare. A report of an unusual case of cilia embedded in posterior retina is presented along with a review of available literature. A 22-year-old male presented with a history of diminished vision and metamorphopsia 1 month after the successful repair of an ocular perforation. Anterior segment examination revealed a sutured superotemporal limbal tear with a surgical iris coloboma and a normally positioned clear lens. Ophthalmoscopic examination revealed a normal optic disc, macular striations and 2 cilia embedded in the retina approximately 2 disc diameters superotemporal to fovea. Vitrectomy with removal of cilia and endolaser was performed. This unusual case shows that cilia may become embedded intraocularly during an ocular perforation and that transvitreal removal may be a preferred mode of therapy with the availability of sophisticated vitreoretinal instrumentation.