Brain morphology in Klinefelter syndrome: extra X chromosome and testosterone supplementation

Neurology. 2000 Jun 27;54(12):2218-23. doi: 10.1212/wnl.54.12.2218.

Abstract

Objective: This study focuses on variation in brain morphology associated with supernumerary X chromosome and Klinefelter syndrome (KS). Using an unselected birth cohort of KS subjects and high-resolution MRI, the authors investigated the neuroanatomic consequences of the 47,XXY karyotype in the presence and absence of exogenous testosterone supplementation.

Methods: Regional brain volumes were measured in 10 subjects with KS and 10 age-matched control men. Five of the KS subjects had received testosterone supplementation since puberty (KS+T) and five had not (KS-T).

Results: KS subjects showed significant (p < 0.01) reduction in left temporal lobe gray matter volumes compared with normal control subjects. Differences in left temporal gray volumes were also significant between the KS+T and KS-T groups (p < 0.01). Verbal fluency scores were significantly different between the KS+T and KS-T groups as well.

Conclusion: Supernumerary X chromosome material in men is associated with a reduction in left temporal lobe gray matter, a finding that is consistent with the verbal and language deficits associated with KS. Also, relative preservation of gray matter in the left temporal region is associated with exposure to exogenous androgen during development. A history of testosterone supplementation also appears to be associated with increased verbal fluency scores in KS patients.

Publication types

  • Clinical Trial
  • Controlled Clinical Trial
  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Adult
  • Analysis of Variance
  • Brain / drug effects
  • Brain / pathology*
  • Cognition Disorders / drug therapy
  • Cognition Disorders / etiology
  • Cognition Disorders / pathology
  • Cohort Studies
  • Humans
  • Intelligence Tests
  • Klinefelter Syndrome / complications
  • Klinefelter Syndrome / drug therapy
  • Klinefelter Syndrome / genetics
  • Klinefelter Syndrome / pathology*
  • Magnetic Resonance Imaging
  • Male
  • Speech Disorders / drug therapy
  • Speech Disorders / etiology*
  • Speech Disorders / pathology
  • Temporal Lobe / drug effects
  • Temporal Lobe / pathology
  • Testosterone / therapeutic use*
  • X Chromosome*

Substances

  • Testosterone