Rationale: Cervical chondrocutaneous branchial remnants are rare, benign, congenital anomalies, frequently seen bilaterally.
Patient concerns: Here, we report the case of a 4-month-old female infant who presented with bilateral lower neck skin tag since birth.
Diagnosis and interventions: The patient underwent mass excision. The final pathological diagnosis was bilateral cervical chondrocutaneous branchial remnants with hyaline cartilage.
Outcomes: No complications were observed after excision. One-year follow-up revealed no recurrence.
Lessons: Bilateral chondrocutaneous branchial remnants are rare anomalies. They are often associated with cardiac or genitourinary abnormalities. Therefore, additional preoperative imaging of the abdomen and heart are recommended.